Development and validation of TreatHSP-QoL: a patient-reported outcome measure for health-related quality of life in hereditary spastic paraplegia
Hereditary spastic paraplegia (HSP) is a rare neurodegenerative disease that lacks specific and validated patient-centered outcome measures (PCOMs). We aimed to develop and validate a health-related quality of life (HRQoL) questionnaire specific to HSP (“TreatHSP-QoL”) that could be used as a PCOM....
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| Hauptverfasser: | , , , , , , , , |
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| Dokumenttyp: | Article (Journal) |
| Sprache: | Englisch |
| Veröffentlicht: |
02 January 2024
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| In: |
Orphanet journal of rare diseases
Year: 2024, Jahrgang: 19, Pages: 1-14 |
| ISSN: | 1750-1172 |
| DOI: | 10.1186/s13023-023-03012-w |
| Online-Zugang: | Verlag, kostenfrei, Volltext: https://doi.org/10.1186/s13023-023-03012-w Verlag, kostenfrei, Volltext: https://ojrd.biomedcentral.com/articles/10.1186/s13023-023-03012-w 
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| Verfasserangaben: | Jekaterina Malina, Eva-Maria Huessler, Karl-Heinz Jöckel, Eva Boog-Whiteside, Nicole Jeschonneck, Bernadette Schröder, Rebecca Schüle, Tobias Kühl and Stephan Klebe |
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